Ageing processes and late manifestations in congenitally deafblind adults in Denmark.

Main results from survey conducted by the Information Centre on Congenital Deafblindness

From: http://www.nud.dk/CA3FE0DA-3DA3-4717-B77B-75D40F2B55BA

 

The Information Centre on Congenital Deafblindness in Denmark has conducted a survey starting in 1999. This article summarises the complete report, which is written in Danish. Birthe Laustrup, director of Information Centre

 

All persons aged 18 and more diagnosed with congenital deafblindness in Denmark are included in the survey of ageing processes and late manifestations (i.e. a connection between the cause of congenital deafblindness and the occurred condition) which has been undertaken by the information Centre, 58 individuals in total. The survey has compared 26 individuals diagnosed with congenital rubella syndrome to 32 individuals

with other aetiologies. The statistical data is therefore organised in a "rubella group" and a "non-rubella group". 53 of the 58 informants stated that the aetiology was known. 2/3 of the target group live in residential settings for congenitally deafblind persons, the last third live together with person with other impairments.

 

In this article some of the main results from the survey are highlighted. When in the following the term both groups is used, variables applicable to both the rubella group and the non-rubella group are referred to

 

Medical and physiological information

In both group there is a high incidence of persons born small for date (born at term, but with lower birth weight than expected). The rubella group has more males than the non-rubella group. In both groups there are many individuals who later in life experience weight problems. In the group non-rubella, it is typically a problem of undesired weight loss. In the persons with congenital rubella syndrome the problem is rather overweight in adult age According to the data collected the problems of weight gain is of a scale which calls for further investigation to identify the causes of this.

 

Congenital hart failure primarily occurs in the rubella group. With early surgery, the heart defects poses no problems for the individuals later in life.

 

If we look at the motor functions and physical impairments present at birth, these only occur in the non-rubella group. In both groups there are individuals who later in life experience physiological deterioration to an extent that they need assistive devices for mobility functions. In the group non rubella this deterioration takes place early in life, as the development of physical impairments in the rubella group only takes place from age

30 and onwards. This may indicate the presence of a late manifestation. In both groups there is a relatively high incidence (15,5%) of muscular deterioration and poor balance in adult age. This underpins that congenitally deafblind persons need treatment from physiotherapists and occupational therapists in their adult age.

 

Vision and hearing

The majority of the informants in both groups have a visual impairment which was diagnosed during the first year of life. Around 2/3 of the population with congenital deafblindness have a progressive vision loss (like glaucoma, retinal detachment, decreasing visual field, and removal of eye), just like we also can rate the generally occurring age related changes in vision to much the same level in both groups. In both groups individuals have severe hearing losses or deafness (the latter is more frequent). Moderate hearing losses are only identified in the group non-rubella. Both groups show that the hearing impairments are identified later than the visual impairments. Individuals in the group non-rubella are generally diagnosed earlier than individuals

in the rubella group. This finding may surprise, as the congenital cataract, possibly in combination with low birth weight and heart failure should cause suspicion of a concurrent hearing loss caused by a rubella virus infection. According to our information 50 persons have had a hearing aid at the time they were diagnosed. Today only 16 individuals still wear their hearing aids. Progressive hearing losses are identified in both groups. However, the prevalence of progressive hearing losses may be higher than shown in the data collected, as unlike progressions in vision losses, the progressions in hearing losses will not immediately be detected in observations of changes in behaviour. For this very reason it seems alarming that control examinations are not being undertaken at regular intervals. With regard to hearing and vision losses the survey documents that the awareness of the risk of progression in the sensory impairments is lacking in the environments where congenitally deafblind adults live. The survey also indicates that there is more awareness of the possibilities of decrease in vision, as ever second individual regularly is taken for eye examinations, and only one in five gets the hearing checked.

 

Hormonal conditions

Problems with metabolism are a known late manifestation of Down syndrome, and have been mentioned as a late manifestation of congenital rubella syndrome as well in foreign studies. None of the informants in the Danish survey has reported any diagnoses with regard to metabolism, so it may seem not to be a matter of late manifestation. Nevertheless we must state from the data collected that 10 out of the 20 individuals in the rubella group have overweight and in the same 10 persons between 2 and 6 symptoms of low metabolism (e.g. tiredness, sadness, increase in emotional instability, passivity,

less stamina and weight gain) are reported. Foreign studies demonstrate that congenital rubella syndrome entails a major risk of developing diabetes. In our survey we identified a few cases of diabetes (3), and in the rubella group only. Whether this finding is a statistical coincidence, or it actually expresses a late manifestation cannot be judged from the present study. Growth retardation has been mentioned as a specific problem in persons born with rubella syndrome. We have identified cases of growth retardation in both groups, but the prevalence is clearly higher in the rubella

group.

 

Neuropsychological conditions

Epilepsy according to our information occurs with almost identical frequency in both groups, but the age of diagnosis is different. In the group non-rubella the epilepsy is diagnosed at an early age and must be considered a part of the clinical picture. The reports on individuals having epilepsy in the rubella group confirm the assumption that epilepsy is a late manifestation likely to appear in the teens. In our survey we have also asked for information on changes in neuropsychological phenomena like attention, concentration and memory. Here we speak of distinct differences in the two groups, as decreased ability in these three functions is remarkably more frequent in the rubella group. The Danish survey, which comprises all aetiologies present in our country among persons with congenital deafblindness, shows that reductions in memory and attention are late manifestations significant to the diagnosis congenital rubella syndrome. A number of individuals in the group non-rubella also report increasing problems with concentration, thus the difference between the two groups is less significant. Development of behaviour problems In our survey we have asked for information on changes in behaviour in 11 different areas. In six of the areas there is a dominant score of individuals with congenital rubella syndrome. Self-stimulating behaviour, motor agitation and increased self-abusive behaviour are three types of behaviour which primarily are  identified in the rubella group. This tendency seems to confirm the hypotheses of a late manifestation with respect to an increase in these types of behaviour. There is a significant difference between the two groups. Increased aggressiveness, less tolerance to changes in routines and increased level of confusion are three types of behaviour which have previously been considered as late manifestations of congenital rubella syndrome. These behaviours are relatively frequent in both groups, however, with the difference that aggressiveness and less tolerance to changes in routines are much more significant in the rubella group, which could indicate a connection with the diagnosis. There is also the possible explanation that these three types of behaviour express general deprivation in the congenitally deafblind persons, or are related to early ageing processes. We know from gerontology that the behaviours mentioned may be observed also in the normal ageing process. Increased restlessness and increased impulsivity are described as late manifestations of congenital rubella syndrome in previous foreign studies. Our study cannot confirm this. According to our data increased restlessness and increased impulsivity is reported in both groups, but not extensively. These behaviours are also known from gerontology. Less initiative, fall in ability to start activity, as well as more difficulties in changing fromone activity to another are also behaviours which previous studies have characterised as late manifestations of congenital rubella syndrome. However, none of these types of behaviour seem to be characteristic of any of the two groups in our study. Despite a small majority of rubella persons showing these behaviours our data cannot confirm previous assumptions. According to our information theses variables covariate. As these behaviours are also described in gerontology, they may be indicators of early ageing processes. Among people who work with congenitally deafblind persons it has often been discussed whether these types of problem behaviour could be explained by environmental factors. We have therefore tried to identify possible

common features of the persons and their environment when the focused behaviours occur. None of them seems to depend on whether the setting is deafblind specific or not. Nor can we state a correlation with the individual's general level of functioning or ability to communicate. 

 

Psychological state and psycho-socially conditioned factors

The study investigated in total 11 types of behaviours. Two of these are low frequent in both groups. Five of the nine variables left show moderate frequency in the behaviours scored with much the same level in the two groups. Four variables have scores in both groups, but clearly higher for the rubella group.

 

Emotional withdrawal and increased separation anxiety are, according to the findings in our study, not particularly a problem among congenitally deafblind adults. If, however, we look at social withdrawal, more frequent waves of sobs and increased passivity, these types of behaviour are a problem to one in five congenitally deafblind persons, with nearly the same occurrence in the two groups. As these behaviours also are known in gerontology, they may be tokens of early ageing. Less energy seems to be a problem to every third congenitally adult person in both groups. We cannot find a clear explanation to this. Could it be the lifelong deprivation caused by the deafblindness? Is this also signs of early ageing? Could the explanation be something so simple as too little exercise? The risk of developing a psychiatric disease is relatively high in both groups. The only difference between the groups, which can be stated, is that the disease is diagnosed at an earlier age in the non-rubella group. Depression is the most frequent diagnoses in both groups. Is this caused by a permanent state of deprivation or is it again due to early ageing? Emotional instability occurs more frequently in the rubella group than in the non-rubella group, we speak of every second individual with congenital rubella syndrome and one in four of the deafblind persons with other aetiologies. The same is manifested for the variable lowered frustration threshold; again the problem is present in every second individual with congenital rubella syndrome and in one in four in the non-rubella group. Do we speak of a late manifestation in the rubella group? Or do we speak of a symptom of early ageing in the rubella group?

 

Sleeping disorders, sleeps only a little and circadian problems. Here we see a significant difference between the two groups. Every second individual in the rubella roup experience considerable sleeping disorders, whilst in the non-rubella group we speak of one in six. The absence of residual vision affects the individuals in the rubella group most. In this group the data monitors a significant correlation between early infection during gestation and severe sleeping disorders later in life. The individuals among whom we have rated all these problem behaviours constitute a representative section of the congenitally deafblind adult population in Denmark. Viewed from the level of functioning the group studied is also highly representative, apart from those individuals who manifested sleeping disorders. They are basically persons who to a certain extent are able to communicate in a linguistic way with their environments.

 

Concluding comments

The changes in behaviour observed in the rubella group to be significantly different from the non-rubella group may indicate rubella specific late manifestation of the congenital syndrome. Changes of neurological or physiological characters take place in some of the organs of these individuals, which result in the onset of problems at somatic, behavioural and psychosocial levels in adult age. Some indications may point to earlier ageing in the rubella group than in other persons. When facing changes in behaviour we must question whether internal factors, external factors or a combination of those are the trigger of the changes observed. At first it must be clarified if the cause could be a yet not discovered somatic condition, a neurological condition or decrease in hearing and/or vision. Attention must be paid to the either sudden or gradual character of the changes observed. A neurological and psychological assessment is also important, and the individuals' interaction with their environments must be observed and analysed as a part of the total evaluation of the persons' situation. We still recommend annual health checks for all persons with congenital rubella syndrome. In its Appendix 2 the report offers a guiding checklist, which may be presented to the physician examining the rubella person. Also we again stress the importance of regular appointments for examinations of hearing and vision. In general there is a need for far more attention to the risk of deteriorations in the two senses for the deafblind population as a whole.

 

If we look at how quickly changes take place in the two groups studied with respect to the variables scored, it appears that within the two-year period our survey went on the positives occur almost exclusively in the rubella group (reported in Appendix 3). If this is a valid tendency we can estimate that only in five years the differences between the two groups compared will be even more important. The Information Centre on Congenital Deafblindness therefore recommends that the results achieved in the present survey should be followed-up by a quantitative study of the same group of individuals starting no later than 2006. Until then qualitatively oriented interviews may contribute to the development of the existing knowledge in identifying useful details from selected informants. Experience based development is still needed in this very important area, with advantage in a combination with medical research. Systematic information of this kind would be highly valuable to the clinical work in our field and considerably contribute to an increased quality of life for the individual adult person with congenital deafblindness.